Diffuse hemangiolymphangioma of small bowel-rare cause of obscure gastrointestinal bleeding

Authors

  • Sudhagar Rengasamy Institute of Surgical Gastroenterology and Liver Transplantation, Government Stanley Medical College, Chennai, Tamil Nadu, India
  • Murugesan Satish Devakumar Institute of Surgical Gastroenterology and Liver Transplantation, Government Stanley Medical College, Chennai, Tamil Nadu, India
  • Anbalagan Amudhan Institute of Surgical Gastroenterology and Liver Transplantation, Government Stanley Medical College, Chennai, Tamil Nadu, India
  • R. Kamalakannan Institute of Surgical Gastroenterology and Liver Transplantation, Government Stanley Medical College, Chennai, Tamil Nadu, India
  • Selvaraj Thangasamy Institute of Surgical Gastroenterology and Liver Transplantation, Government Stanley Medical College, Chennai, Tamil Nadu, India
  • Jeswanth Sathyanesan Institute of Surgical Gastroenterology and Liver Transplantation, Government Stanley Medical College, Chennai, Tamil Nadu, India

DOI:

https://doi.org/10.18203/2349-2902.isj20220350

Keywords:

HL, Small bowel, GI bleeding

Abstract

Hemangiolymphangioma (HL) is a rare benign tumor, commonly present in pediatric age group that involves the head and neck. Small bowel HL has been reported as solitary or segmental involvement. Here we report a case of diffuse small bowel HL, presented as chronic anemia, fatigability and obscure gastrointestinal (GI) bleeding. A 42-year male presented with 15 years history of bleeding per rectum, anemia, and fatigability, received multiple blood transfusions. The exact cause could not be identified. His complete hemogram parameters were low requiring further imaging studies. Imaging and intraoperative enteroscopy showed multiple nodular lesions in mesentry as well as in the mucosa of the entire small bowel. Bleeding points were noted in a proximal jejunal lesion which was resected. Histopathological study confirmed as benign HL. HL are rare tumors of gastrointestinal tract. To the best of our knowledge diffuse HL of the small bowel have not been reported in the medical literature. With this case scenario, one should consider these tumors in the differential diagnosis of obscure lower GI bleed and chronic anemia, as well as explore definitive management options for these benign symptomatic tumors.

Author Biographies

Sudhagar Rengasamy, Institute of Surgical Gastroenterology and Liver Transplantation, Government Stanley Medical College, Chennai, Tamil Nadu, India

Department of Surgical Gastroenterology,

Murugesan Satish Devakumar, Institute of Surgical Gastroenterology and Liver Transplantation, Government Stanley Medical College, Chennai, Tamil Nadu, India

Assistant Professor, Department of Surgical Gastroenterology,

Anbalagan Amudhan, Institute of Surgical Gastroenterology and Liver Transplantation, Government Stanley Medical College, Chennai, Tamil Nadu, India

Assistant Professor, Department of Surgical Gastroenterology,

R. Kamalakannan, Institute of Surgical Gastroenterology and Liver Transplantation, Government Stanley Medical College, Chennai, Tamil Nadu, India

Assistant Professor, Department of Surgical Gastroenterology,

Selvaraj Thangasamy, Institute of Surgical Gastroenterology and Liver Transplantation, Government Stanley Medical College, Chennai, Tamil Nadu, India

Associate Professor, Department of Surgical Gastroenterology,

Jeswanth Sathyanesan, Institute of Surgical Gastroenterology and Liver Transplantation, Government Stanley Medical College, Chennai, Tamil Nadu, India

Director and Head,

Institute of Surgical Gastroenterology & Liver Transplantation

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Published

2022-01-29

Issue

Section

Case Reports